Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature

Leiomyosarcoma (LMS) is an uncommon malignant spindle cell neoplasm of smooth muscles, accounting approximately 7% of soft tissue sarcoma. Primary LMS involving bone is an exceptional entity with very few cases described in the literature. The clinical, imaging, and pathological findings were analyz...

Full description

Saved in:
Bibliographic Details
Main Authors: Jitin Goyal, Bineeta Parihar, Nitin Agarwal, Sulagna Manna, Anila Sharma, Sunil Kumar Puri
Format: Article
Language:English
Published: Thieme Medical and Scientific Publishers Pvt. Ltd.
Series:Indian Journal of Medical and Paediatric Oncology
Subjects:
Online Access:http://www.thieme-connect.de/DOI/DOI?10.1055/s-0045-1801882
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849337568744701952
author Jitin Goyal
Bineeta Parihar
Nitin Agarwal
Sulagna Manna
Anila Sharma
Sunil Kumar Puri
author_facet Jitin Goyal
Bineeta Parihar
Nitin Agarwal
Sulagna Manna
Anila Sharma
Sunil Kumar Puri
author_sort Jitin Goyal
collection DOAJ
description Leiomyosarcoma (LMS) is an uncommon malignant spindle cell neoplasm of smooth muscles, accounting approximately 7% of soft tissue sarcoma. Primary LMS involving bone is an exceptional entity with very few cases described in the literature. The clinical, imaging, and pathological findings were analyzed retrospectively in three confirmed cases of primary LMS of bone. Pain and swelling were the patients' clinical symptoms. On imaging, LMS was often described as a solitary ill-defined lytic lesion with cortical breach depicted on radiograph or computed tomography (CT) scan. Magnetic resonance imaging (MRI) reveals a heterogeneous intermediate-hyperintense signal lesion on T2-weighted imaging (T2WI) with postcontrast enhancement. Histopathology reveals spindle cells arranged in fascicles with nuclear atypia and smooth muscle actin (SMA) positivity on immunohistochemistry (IHC)—consistent with diagnosis of LMS. The patients underwent surgical gross total resection with curative intent, followed by adjuvant chemotherapy or radiotherapy depending upon the stage and histological grade of LMS. On follow-up, the patients were disease free with no evidence of recurrence.
format Article
id doaj-art-b02ef4f15a7f44f9b698d41c543d2e08
institution Kabale University
issn 0971-5851
0975-2129
language English
publisher Thieme Medical and Scientific Publishers Pvt. Ltd.
record_format Article
series Indian Journal of Medical and Paediatric Oncology
spelling doaj-art-b02ef4f15a7f44f9b698d41c543d2e082025-08-20T03:44:39ZengThieme Medical and Scientific Publishers Pvt. Ltd.Indian Journal of Medical and Paediatric Oncology0971-58510975-212910.1055/s-0045-1801882Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of LiteratureJitin Goyal0https://orcid.org/0000-0001-9037-9031Bineeta Parihar1Nitin Agarwal2Sulagna Manna3Anila Sharma4Sunil Kumar Puri5Department of Radiology, Rajiv Gandhi Cancer Institute and Research Centre, Delhi, IndiaDepartment of Radiology, Rajiv Gandhi Cancer Institute and Research Centre, Delhi, IndiaDepartment of Radiology, Rajiv Gandhi Cancer Institute and Research Centre, Delhi, IndiaDepartment of Pathology; Rajiv Gandhi Cancer Institute and Research Centre, DelhiDepartment of Pathology; Rajiv Gandhi Cancer Institute and Research Centre, DelhiDepartment of Radiology, Rajiv Gandhi Cancer Institute and Research Centre, Delhi, IndiaLeiomyosarcoma (LMS) is an uncommon malignant spindle cell neoplasm of smooth muscles, accounting approximately 7% of soft tissue sarcoma. Primary LMS involving bone is an exceptional entity with very few cases described in the literature. The clinical, imaging, and pathological findings were analyzed retrospectively in three confirmed cases of primary LMS of bone. Pain and swelling were the patients' clinical symptoms. On imaging, LMS was often described as a solitary ill-defined lytic lesion with cortical breach depicted on radiograph or computed tomography (CT) scan. Magnetic resonance imaging (MRI) reveals a heterogeneous intermediate-hyperintense signal lesion on T2-weighted imaging (T2WI) with postcontrast enhancement. Histopathology reveals spindle cells arranged in fascicles with nuclear atypia and smooth muscle actin (SMA) positivity on immunohistochemistry (IHC)—consistent with diagnosis of LMS. The patients underwent surgical gross total resection with curative intent, followed by adjuvant chemotherapy or radiotherapy depending upon the stage and histological grade of LMS. On follow-up, the patients were disease free with no evidence of recurrence.http://www.thieme-connect.de/DOI/DOI?10.1055/s-0045-1801882leiomyosarcomaimmunohistochemistryMRIPET-CTcase series
spellingShingle Jitin Goyal
Bineeta Parihar
Nitin Agarwal
Sulagna Manna
Anila Sharma
Sunil Kumar Puri
Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
Indian Journal of Medical and Paediatric Oncology
leiomyosarcoma
immunohistochemistry
MRI
PET-CT
case series
title Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
title_full Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
title_fullStr Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
title_full_unstemmed Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
title_short Primary Leiomyosarcoma of Bone: A Rare Case Series with Review of Literature
title_sort primary leiomyosarcoma of bone a rare case series with review of literature
topic leiomyosarcoma
immunohistochemistry
MRI
PET-CT
case series
url http://www.thieme-connect.de/DOI/DOI?10.1055/s-0045-1801882
work_keys_str_mv AT jitingoyal primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature
AT bineetaparihar primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature
AT nitinagarwal primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature
AT sulagnamanna primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature
AT anilasharma primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature
AT sunilkumarpuri primaryleiomyosarcomaofboneararecaseserieswithreviewofliterature