Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error

Background: The relationship between inborn errors of immunity (IEIs) and COVID-19 severity and incidence rates remains unclear due to limited and diverse data. This study aimed to address this gap by identifying specific IEIs associated with an increased risk of severe COVID-19 or a predisposition...

Full description

Saved in:
Bibliographic Details
Main Authors: Negin Salemi, Behrokh Shojaie, Paria Bolourinejad, Roya Sherkat, Aryana Zamanifar, Farhoodeh Ghaedrahmati, Mahdieh Azizi, Hamid Aria
Format: Article
Language:English
Published: Wolters Kluwer Medknow Publications 2024-11-01
Series:Advanced Biomedical Research
Subjects:
Online Access:https://journals.lww.com/10.4103/abr.abr_134_23
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1846134521622167552
author Negin Salemi
Behrokh Shojaie
Paria Bolourinejad
Roya Sherkat
Aryana Zamanifar
Farhoodeh Ghaedrahmati
Mahdieh Azizi
Hamid Aria
author_facet Negin Salemi
Behrokh Shojaie
Paria Bolourinejad
Roya Sherkat
Aryana Zamanifar
Farhoodeh Ghaedrahmati
Mahdieh Azizi
Hamid Aria
author_sort Negin Salemi
collection DOAJ
description Background: The relationship between inborn errors of immunity (IEIs) and COVID-19 severity and incidence rates remains unclear due to limited and diverse data. This study aimed to address this gap by identifying specific IEIs associated with an increased risk of severe COVID-19 or a predisposition to severe disease before vaccination. Materials and Methods: Data were collected from the medical records of 15 patients with various IEIs, supplemented by interviews with individuals from an IEIs registry who had experienced COVID-19 before vaccination. Results: Among the participants, only three patients (20%) experienced severe-prolonged COVID-19. Notably, this severity was predominantly observed in two male patients with Bruton’s disease (BD) and one female patient with autosomal recessive hypogammaglobinemia. Moderate and severe COVID-19 cases were equally distributed (13.33%). In the female subgroup, one patient with common variable immunodeficiency and another with combined immunodeficiency experienced moderate and severe COVID-19, respectively. Conversely, both male patients with moderate and severe COVID-19 had BD. Conclusion: Despite the limited number of severe cases, the absence of cytokine storm manifestation suggests potential protective mechanisms, possibly due to intravenous immunoglobulin therapy and inherent deficiencies within cytokine-producing cells (B and T cells). While IEIs may not be significant risk factors for COVID-19, they offer promising avenues for further research into therapeutic strategies targeting specific immune system components to mitigate severe COVID-19.
format Article
id doaj-art-f84e1a403e3c4975919a5bda5ecfede8
institution Kabale University
issn 2277-9175
language English
publishDate 2024-11-01
publisher Wolters Kluwer Medknow Publications
record_format Article
series Advanced Biomedical Research
spelling doaj-art-f84e1a403e3c4975919a5bda5ecfede82024-12-09T13:10:02ZengWolters Kluwer Medknow PublicationsAdvanced Biomedical Research2277-91752024-11-0113111211210.4103/abr.abr_134_23Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of ErrorNegin SalemiBehrokh ShojaieParia BolourinejadRoya SherkatAryana ZamanifarFarhoodeh GhaedrahmatiMahdieh AziziHamid AriaBackground: The relationship between inborn errors of immunity (IEIs) and COVID-19 severity and incidence rates remains unclear due to limited and diverse data. This study aimed to address this gap by identifying specific IEIs associated with an increased risk of severe COVID-19 or a predisposition to severe disease before vaccination. Materials and Methods: Data were collected from the medical records of 15 patients with various IEIs, supplemented by interviews with individuals from an IEIs registry who had experienced COVID-19 before vaccination. Results: Among the participants, only three patients (20%) experienced severe-prolonged COVID-19. Notably, this severity was predominantly observed in two male patients with Bruton’s disease (BD) and one female patient with autosomal recessive hypogammaglobinemia. Moderate and severe COVID-19 cases were equally distributed (13.33%). In the female subgroup, one patient with common variable immunodeficiency and another with combined immunodeficiency experienced moderate and severe COVID-19, respectively. Conversely, both male patients with moderate and severe COVID-19 had BD. Conclusion: Despite the limited number of severe cases, the absence of cytokine storm manifestation suggests potential protective mechanisms, possibly due to intravenous immunoglobulin therapy and inherent deficiencies within cytokine-producing cells (B and T cells). While IEIs may not be significant risk factors for COVID-19, they offer promising avenues for further research into therapeutic strategies targeting specific immune system components to mitigate severe COVID-19.https://journals.lww.com/10.4103/abr.abr_134_23agammaglobulinemiacovid-19primary immunodeficiency diseasesars-cov-2
spellingShingle Negin Salemi
Behrokh Shojaie
Paria Bolourinejad
Roya Sherkat
Aryana Zamanifar
Farhoodeh Ghaedrahmati
Mahdieh Azizi
Hamid Aria
Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
Advanced Biomedical Research
agammaglobulinemia
covid-19
primary immunodeficiency disease
sars-cov-2
title Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
title_full Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
title_fullStr Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
title_full_unstemmed Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
title_short Diversity in the Clinical Course and Outcome of COVID-19 in Patients with Different Inborn Errors of Immunity can be Associated with the Type of Error
title_sort diversity in the clinical course and outcome of covid 19 in patients with different inborn errors of immunity can be associated with the type of error
topic agammaglobulinemia
covid-19
primary immunodeficiency disease
sars-cov-2
url https://journals.lww.com/10.4103/abr.abr_134_23
work_keys_str_mv AT neginsalemi diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT behrokhshojaie diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT pariabolourinejad diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT royasherkat diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT aryanazamanifar diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT farhoodehghaedrahmati diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT mahdiehazizi diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror
AT hamidaria diversityintheclinicalcourseandoutcomeofcovid19inpatientswithdifferentinbornerrorsofimmunitycanbeassociatedwiththetypeoferror