SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias

Abstract Catecholaminergic polymorphic ventricular tachycardia (CPVT) is a stress‐provoked ventricular arrhythmia, which also manifests sinoatrial node (SAN) dysfunction. We recently showed that SK4 calcium‐activated potassium channels are important for automaticity of cardiomyocytes derived from hu...

Full description

Saved in:
Bibliographic Details
Main Authors: Shiraz Haron‐Khun, David Weisbrod, Hanna Bueno, Dor Yadin, Joachim Behar, Asher Peretz, Ofer Binah, Edith Hochhauser, Michael Eldar, Yael Yaniv, Michael Arad, Bernard Attali
Format: Article
Language:English
Published: Springer Nature 2017-02-01
Series:EMBO Molecular Medicine
Subjects:
Online Access:https://doi.org/10.15252/emmm.201606937
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849342182458130432
author Shiraz Haron‐Khun
David Weisbrod
Hanna Bueno
Dor Yadin
Joachim Behar
Asher Peretz
Ofer Binah
Edith Hochhauser
Michael Eldar
Yael Yaniv
Michael Arad
Bernard Attali
author_facet Shiraz Haron‐Khun
David Weisbrod
Hanna Bueno
Dor Yadin
Joachim Behar
Asher Peretz
Ofer Binah
Edith Hochhauser
Michael Eldar
Yael Yaniv
Michael Arad
Bernard Attali
author_sort Shiraz Haron‐Khun
collection DOAJ
description Abstract Catecholaminergic polymorphic ventricular tachycardia (CPVT) is a stress‐provoked ventricular arrhythmia, which also manifests sinoatrial node (SAN) dysfunction. We recently showed that SK4 calcium‐activated potassium channels are important for automaticity of cardiomyocytes derived from human embryonic stem cells. Here SK4 channels were identified in human induced pluripotent stem cell‐derived cardiomyocytes (hiPSC‐CMs) from healthy and CPVT2 patients bearing a mutation in calsequestrin 2 (CASQ2‐D307H) and in SAN cells from WT and CASQ2‐D307H knock‐in (KI) mice. TRAM‐34, a selective blocker of SK4 channels, prominently reduced delayed afterdepolarizations and arrhythmic Ca2+ transients observed following application of the β‐adrenergic agonist isoproterenol in CPVT2‐derived hiPSC‐CMs and in SAN cells from KI mice. Strikingly, in vivo ECG recording showed that intraperitoneal injection of the SK4 channel blockers, TRAM‐34 or clotrimazole, greatly reduced the arrhythmic features of CASQ2‐D307H KI and CASQ2 knockout mice at rest and following exercise. This work demonstrates the critical role of SK4 Ca2+‐activated K+ channels in adult pacemaker function, making them promising therapeutic targets for the treatment of cardiac ventricular arrhythmias such as CPVT.
format Article
id doaj-art-f81d60e628cd448aa9f2afc49e1e9d69
institution Kabale University
issn 1757-4676
1757-4684
language English
publishDate 2017-02-01
publisher Springer Nature
record_format Article
series EMBO Molecular Medicine
spelling doaj-art-f81d60e628cd448aa9f2afc49e1e9d692025-08-20T03:43:29ZengSpringer NatureEMBO Molecular Medicine1757-46761757-46842017-02-019441542910.15252/emmm.201606937SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmiasShiraz Haron‐Khun0David Weisbrod1Hanna Bueno2Dor Yadin3Joachim Behar4Asher Peretz5Ofer Binah6Edith Hochhauser7Michael Eldar8Yael Yaniv9Michael Arad10Bernard Attali11Department of Physiology and Pharmacology, The Sackler Faculty of Medicine, Tel Aviv UniversityDepartment of Physiology and Pharmacology, The Sackler Faculty of Medicine, Tel Aviv UniversityDepartment of Physiology and Pharmacology, The Sackler Faculty of Medicine, Tel Aviv UniversityLeviev Heart Center, Sheba Medical Center, Tel HashomerLaboratory of Bioenergetic and Bioelectric Systems, Biomedical Engineering Faculty, Technion—Israel Institute of TechnologyDepartment of Physiology and Pharmacology, The Sackler Faculty of Medicine, Tel Aviv UniversityDepartment of Physiology, Ruth & Bruce Rappaport Faculty of Medicine, Technion—Israel Institute of TechnologyThe Cardiac Research Laboratory of the Department of Cardiothoracic Surgery, Felsenstein Medical Research Center, Rabin Medical Center, Tel Aviv UniversityLeviev Heart Center, Sheba Medical Center, Tel HashomerLaboratory of Bioenergetic and Bioelectric Systems, Biomedical Engineering Faculty, Technion—Israel Institute of TechnologyLeviev Heart Center, Sheba Medical Center, Tel HashomerDepartment of Physiology and Pharmacology, The Sackler Faculty of Medicine, Tel Aviv UniversityAbstract Catecholaminergic polymorphic ventricular tachycardia (CPVT) is a stress‐provoked ventricular arrhythmia, which also manifests sinoatrial node (SAN) dysfunction. We recently showed that SK4 calcium‐activated potassium channels are important for automaticity of cardiomyocytes derived from human embryonic stem cells. Here SK4 channels were identified in human induced pluripotent stem cell‐derived cardiomyocytes (hiPSC‐CMs) from healthy and CPVT2 patients bearing a mutation in calsequestrin 2 (CASQ2‐D307H) and in SAN cells from WT and CASQ2‐D307H knock‐in (KI) mice. TRAM‐34, a selective blocker of SK4 channels, prominently reduced delayed afterdepolarizations and arrhythmic Ca2+ transients observed following application of the β‐adrenergic agonist isoproterenol in CPVT2‐derived hiPSC‐CMs and in SAN cells from KI mice. Strikingly, in vivo ECG recording showed that intraperitoneal injection of the SK4 channel blockers, TRAM‐34 or clotrimazole, greatly reduced the arrhythmic features of CASQ2‐D307H KI and CASQ2 knockout mice at rest and following exercise. This work demonstrates the critical role of SK4 Ca2+‐activated K+ channels in adult pacemaker function, making them promising therapeutic targets for the treatment of cardiac ventricular arrhythmias such as CPVT.https://doi.org/10.15252/emmm.201606937cardiac arrhythmiacatecholaminergic polymorphic ventricular tachycardiapacemakerpotassium channelSK4
spellingShingle Shiraz Haron‐Khun
David Weisbrod
Hanna Bueno
Dor Yadin
Joachim Behar
Asher Peretz
Ofer Binah
Edith Hochhauser
Michael Eldar
Yael Yaniv
Michael Arad
Bernard Attali
SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
EMBO Molecular Medicine
cardiac arrhythmia
catecholaminergic polymorphic ventricular tachycardia
pacemaker
potassium channel
SK4
title SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
title_full SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
title_fullStr SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
title_full_unstemmed SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
title_short SK4 K+ channels are therapeutic targets for the treatment of cardiac arrhythmias
title_sort sk4 k channels are therapeutic targets for the treatment of cardiac arrhythmias
topic cardiac arrhythmia
catecholaminergic polymorphic ventricular tachycardia
pacemaker
potassium channel
SK4
url https://doi.org/10.15252/emmm.201606937
work_keys_str_mv AT shirazharonkhun sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT davidweisbrod sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT hannabueno sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT doryadin sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT joachimbehar sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT asherperetz sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT oferbinah sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT edithhochhauser sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT michaeleldar sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT yaelyaniv sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT michaelarad sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias
AT bernardattali sk4kchannelsaretherapeutictargetsforthetreatmentofcardiacarrhythmias