A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.

Immunocompromised individuals are at risk for developing lymphocryptovirus-associated lymphoproliferative diseases, such as Epstein Barr virus (EBV)-associated B cell lymphomas and post-transplant lymphoproliferative disorder (PTLD). We previously reported development of cynomolgus lymphocryptovirus...

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Main Authors: Helen L Wu, Whitney C Weber, Courtney M Waytashek, Carla D Boyle, Jason S Reed, Katherine B Bateman, Hannah K Fisher, Yan Chen, Kimberly Armantrout, Tonya Swanson, Christine Shriver-Munsch, Mina Northrup, Miranda Fischer, Sreya Biswas, John Templon, Angela Panoskaltsis-Mortari, Benjamin J Burwitz, Amanda L Johnson, Lois Colgin, Anne D Lewis, Jeremy V Smedley, Michael K Axthelm, Rebecca Skalsky, Gabrielle Meyers, Richard T Maziarz, Erik Mittra, Melissa Berg, Jeffrey J Stanton, Jonah B Sacha
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2024-11-01
Series:PLoS Pathogens
Online Access:https://doi.org/10.1371/journal.ppat.1012644
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author Helen L Wu
Whitney C Weber
Courtney M Waytashek
Carla D Boyle
Jason S Reed
Katherine B Bateman
Hannah K Fisher
Yan Chen
Kimberly Armantrout
Tonya Swanson
Christine Shriver-Munsch
Mina Northrup
Miranda Fischer
Sreya Biswas
John Templon
Angela Panoskaltsis-Mortari
Benjamin J Burwitz
Amanda L Johnson
Lois Colgin
Anne D Lewis
Jeremy V Smedley
Michael K Axthelm
Rebecca Skalsky
Gabrielle Meyers
Richard T Maziarz
Erik Mittra
Melissa Berg
Jeffrey J Stanton
Jonah B Sacha
author_facet Helen L Wu
Whitney C Weber
Courtney M Waytashek
Carla D Boyle
Jason S Reed
Katherine B Bateman
Hannah K Fisher
Yan Chen
Kimberly Armantrout
Tonya Swanson
Christine Shriver-Munsch
Mina Northrup
Miranda Fischer
Sreya Biswas
John Templon
Angela Panoskaltsis-Mortari
Benjamin J Burwitz
Amanda L Johnson
Lois Colgin
Anne D Lewis
Jeremy V Smedley
Michael K Axthelm
Rebecca Skalsky
Gabrielle Meyers
Richard T Maziarz
Erik Mittra
Melissa Berg
Jeffrey J Stanton
Jonah B Sacha
author_sort Helen L Wu
collection DOAJ
description Immunocompromised individuals are at risk for developing lymphocryptovirus-associated lymphoproliferative diseases, such as Epstein Barr virus (EBV)-associated B cell lymphomas and post-transplant lymphoproliferative disorder (PTLD). We previously reported development of cynomolgus lymphocryptovirus (CyLCV)-associated PTLD in Mauritian cynomolgus macaques (MCMs) undergoing hematopoietic stem cell transplantation (HSCT), which mirrored EBV-PTLD in transplant patients. Here, we sought to develop a MCM model of lymphocryptovirus-associated lymphoproliferative disease in immunosuppressed MCMs without HSCT. Five simian immunodeficiency virus (SIV)-infected, CD8α+ cell-depleted MCMs received an infusion of autologous B-lymphoblastoid cells transformed with CyLCV, followed by varying degrees of immunosuppression. Four of five infused macaques developed masses coincident with increasing CyLCV plasma viremia, and necropsies confirmed the presence of multicentric lymphomas, which most commonly manifested in lymph nodes, gastrointestinal tract, adrenal glands, and pancreas. Affected tissues harbored neoplastic lymphocytes double-positive for CD20 and CyLCV EBNA2 antigen, large frequencies of proliferating B cells, and high levels of cell-associated CyLCV DNA. In addition, longitudinal 18F-fluorodeoxyglucose positron-emission tomography (18F-FDG PET) of one MCM successfully detected lymphoproliferative disease in the adrenal glands prior to clinical signs of disease. These data demonstrate successful induction of lymphocryptovirus-associated PTLD-like disease in 4 of 5 MCMs, and thus support the use of MCMs as a preclinical NHP model of EBV-associated lymphoproliferative disease that could be employed to test novel diagnostic and therapeutic modalities.
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issn 1553-7366
1553-7374
language English
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publisher Public Library of Science (PLoS)
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spelling doaj-art-e9b7c4d3cacf41f4b7d8c3b2d116c58e2024-11-28T05:31:03ZengPublic Library of Science (PLoS)PLoS Pathogens1553-73661553-73742024-11-012011e101264410.1371/journal.ppat.1012644A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.Helen L WuWhitney C WeberCourtney M WaytashekCarla D BoyleJason S ReedKatherine B BatemanHannah K FisherYan ChenKimberly ArmantroutTonya SwansonChristine Shriver-MunschMina NorthrupMiranda FischerSreya BiswasJohn TemplonAngela Panoskaltsis-MortariBenjamin J BurwitzAmanda L JohnsonLois ColginAnne D LewisJeremy V SmedleyMichael K AxthelmRebecca SkalskyGabrielle MeyersRichard T MaziarzErik MittraMelissa BergJeffrey J StantonJonah B SachaImmunocompromised individuals are at risk for developing lymphocryptovirus-associated lymphoproliferative diseases, such as Epstein Barr virus (EBV)-associated B cell lymphomas and post-transplant lymphoproliferative disorder (PTLD). We previously reported development of cynomolgus lymphocryptovirus (CyLCV)-associated PTLD in Mauritian cynomolgus macaques (MCMs) undergoing hematopoietic stem cell transplantation (HSCT), which mirrored EBV-PTLD in transplant patients. Here, we sought to develop a MCM model of lymphocryptovirus-associated lymphoproliferative disease in immunosuppressed MCMs without HSCT. Five simian immunodeficiency virus (SIV)-infected, CD8α+ cell-depleted MCMs received an infusion of autologous B-lymphoblastoid cells transformed with CyLCV, followed by varying degrees of immunosuppression. Four of five infused macaques developed masses coincident with increasing CyLCV plasma viremia, and necropsies confirmed the presence of multicentric lymphomas, which most commonly manifested in lymph nodes, gastrointestinal tract, adrenal glands, and pancreas. Affected tissues harbored neoplastic lymphocytes double-positive for CD20 and CyLCV EBNA2 antigen, large frequencies of proliferating B cells, and high levels of cell-associated CyLCV DNA. In addition, longitudinal 18F-fluorodeoxyglucose positron-emission tomography (18F-FDG PET) of one MCM successfully detected lymphoproliferative disease in the adrenal glands prior to clinical signs of disease. These data demonstrate successful induction of lymphocryptovirus-associated PTLD-like disease in 4 of 5 MCMs, and thus support the use of MCMs as a preclinical NHP model of EBV-associated lymphoproliferative disease that could be employed to test novel diagnostic and therapeutic modalities.https://doi.org/10.1371/journal.ppat.1012644
spellingShingle Helen L Wu
Whitney C Weber
Courtney M Waytashek
Carla D Boyle
Jason S Reed
Katherine B Bateman
Hannah K Fisher
Yan Chen
Kimberly Armantrout
Tonya Swanson
Christine Shriver-Munsch
Mina Northrup
Miranda Fischer
Sreya Biswas
John Templon
Angela Panoskaltsis-Mortari
Benjamin J Burwitz
Amanda L Johnson
Lois Colgin
Anne D Lewis
Jeremy V Smedley
Michael K Axthelm
Rebecca Skalsky
Gabrielle Meyers
Richard T Maziarz
Erik Mittra
Melissa Berg
Jeffrey J Stanton
Jonah B Sacha
A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
PLoS Pathogens
title A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
title_full A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
title_fullStr A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
title_full_unstemmed A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
title_short A model of lymphocryptovirus-associated post-transplant lymphoproliferative disorder in immunosuppressed Mauritian cynomolgus macaques.
title_sort model of lymphocryptovirus associated post transplant lymphoproliferative disorder in immunosuppressed mauritian cynomolgus macaques
url https://doi.org/10.1371/journal.ppat.1012644
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