Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India

Two distinct and potentially deceitful cases of neurologic melioidosis are reported. Case 1: A 39-year-old alcoholic and uncontrolled diabetic male presented with cough, fever, and left focal seizures with secondary generalization. An magnetic resonance imaging (MRI) brain scan revealed a small per...

Full description

Saved in:
Bibliographic Details
Main Authors: Kavitha Saravu, Rajagopal Kadavigere, Ananthakrishna Barkur Shastry, Rohit Pai, Chiranjay Mukhopadhyay
Format: Article
Language:English
Published: The Journal of Infection in Developing Countries 2015-11-01
Series:Journal of Infection in Developing Countries
Subjects:
Online Access:https://jidc.org/index.php/journal/article/view/6586
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849313736836251648
author Kavitha Saravu
Rajagopal Kadavigere
Ananthakrishna Barkur Shastry
Rohit Pai
Chiranjay Mukhopadhyay
author_facet Kavitha Saravu
Rajagopal Kadavigere
Ananthakrishna Barkur Shastry
Rohit Pai
Chiranjay Mukhopadhyay
author_sort Kavitha Saravu
collection DOAJ
description Two distinct and potentially deceitful cases of neurologic melioidosis are reported. Case 1: A 39-year-old alcoholic and uncontrolled diabetic male presented with cough, fever, and left focal seizures with secondary generalization. An magnetic resonance imaging (MRI) brain scan revealed a small peripherally enhancing subdural collection along the interhemispheric fissure suggestive of minimal subdural empyema. Blood culture grew Burkholderia pseudomallei. Patient was diagnosed with disseminated bacteraemic melioidosis with subdural empyema. He was successfully treated with ceftazidime-cotrimoxazole-doxycycline. Case 2: A 45-year-old male presented with left lower limb weakness, difficulty in passing urine and stool, and back pain radiating to lower limbs. Neurological examination revealed flaccid left lower limb with absent deep tendon reflexes and plantar reflex. Spinal MRI showed T2 hyperintensity from D9 to L1 suggestive of demyelination. Patient was treated with high dose methylprednisolone. By day 3 of steroid treatment, lower limb weakness progressed. Subsequent MRI showed extensive cord hyperintensity on T2 weighted sequence extending from C5 to conus medullaris consistent with demyelination. Cerebrospinal fluid (CSF) culture grew B. pseudomallei, and the patient was given meropenem-cotrimoxazole. After three weeks of parenteral treatment, the lower limbs remained paralyzed. Patient was discharged on oral cotrimoxazole-doxycycline. Conclusions: Melioidosis should be considered as a differential in focal suppurative central nervous system (CNS) lesions, meningoencephalitis, or encephalomyelitis in endemic areas. CNS infections must be ruled out prior to steroid administration. The role of corticosteroids in demyelinating CNS melioidosis has been refuted. This is a rare documentation of effect of unintentional corticosteroid treatment in melioidosis.
format Article
id doaj-art-8e4c51a8f01943a0ac4d859b26aaffb7
institution Kabale University
issn 1972-2680
language English
publishDate 2015-11-01
publisher The Journal of Infection in Developing Countries
record_format Article
series Journal of Infection in Developing Countries
spelling doaj-art-8e4c51a8f01943a0ac4d859b26aaffb72025-08-20T03:52:39ZengThe Journal of Infection in Developing CountriesJournal of Infection in Developing Countries1972-26802015-11-0191110.3855/jidc.6586Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in IndiaKavitha Saravu0Rajagopal Kadavigere1Ananthakrishna Barkur Shastry2Rohit Pai3Chiranjay Mukhopadhyay4Kasturba Medical College, Manipal University, Madhav Nagar, Manipal, IndiaKasturba Medical College, Manipal University, Madhav Nagar, Manipal, IndiaKasturba Medical College, Manipal University, Madhav Nagar, Manipal, IndiaKasturba Medical College, Manipal University, Madhav Nagar, Manipal, IndiaKasturba Medical College, Manipal University, Madhav Nagar, Manipal, IndiaTwo distinct and potentially deceitful cases of neurologic melioidosis are reported. Case 1: A 39-year-old alcoholic and uncontrolled diabetic male presented with cough, fever, and left focal seizures with secondary generalization. An magnetic resonance imaging (MRI) brain scan revealed a small peripherally enhancing subdural collection along the interhemispheric fissure suggestive of minimal subdural empyema. Blood culture grew Burkholderia pseudomallei. Patient was diagnosed with disseminated bacteraemic melioidosis with subdural empyema. He was successfully treated with ceftazidime-cotrimoxazole-doxycycline. Case 2: A 45-year-old male presented with left lower limb weakness, difficulty in passing urine and stool, and back pain radiating to lower limbs. Neurological examination revealed flaccid left lower limb with absent deep tendon reflexes and plantar reflex. Spinal MRI showed T2 hyperintensity from D9 to L1 suggestive of demyelination. Patient was treated with high dose methylprednisolone. By day 3 of steroid treatment, lower limb weakness progressed. Subsequent MRI showed extensive cord hyperintensity on T2 weighted sequence extending from C5 to conus medullaris consistent with demyelination. Cerebrospinal fluid (CSF) culture grew B. pseudomallei, and the patient was given meropenem-cotrimoxazole. After three weeks of parenteral treatment, the lower limbs remained paralyzed. Patient was discharged on oral cotrimoxazole-doxycycline. Conclusions: Melioidosis should be considered as a differential in focal suppurative central nervous system (CNS) lesions, meningoencephalitis, or encephalomyelitis in endemic areas. CNS infections must be ruled out prior to steroid administration. The role of corticosteroids in demyelinating CNS melioidosis has been refuted. This is a rare documentation of effect of unintentional corticosteroid treatment in melioidosis. https://jidc.org/index.php/journal/article/view/6586melioidosisBurkholderia infectionneurologic melioidosis
spellingShingle Kavitha Saravu
Rajagopal Kadavigere
Ananthakrishna Barkur Shastry
Rohit Pai
Chiranjay Mukhopadhyay
Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
Journal of Infection in Developing Countries
melioidosis
Burkholderia infection
neurologic melioidosis
title Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
title_full Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
title_fullStr Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
title_full_unstemmed Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
title_short Neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in India
title_sort neurologic melioidosis presented as encephalomyelitis and subdural collection in two male labourers in india
topic melioidosis
Burkholderia infection
neurologic melioidosis
url https://jidc.org/index.php/journal/article/view/6586
work_keys_str_mv AT kavithasaravu neurologicmelioidosispresentedasencephalomyelitisandsubduralcollectionintwomalelabourersinindia
AT rajagopalkadavigere neurologicmelioidosispresentedasencephalomyelitisandsubduralcollectionintwomalelabourersinindia
AT ananthakrishnabarkurshastry neurologicmelioidosispresentedasencephalomyelitisandsubduralcollectionintwomalelabourersinindia
AT rohitpai neurologicmelioidosispresentedasencephalomyelitisandsubduralcollectionintwomalelabourersinindia
AT chiranjaymukhopadhyay neurologicmelioidosispresentedasencephalomyelitisandsubduralcollectionintwomalelabourersinindia