Core fucosylation of IL-2RB is required for natural killer cell homeostasis

Summary: Natural killer (NK) cell homeostasis and effector functions require context-dependent signaling via numerous receptors, including the interleukin-15 receptor (IL-15R). Post-translational modifications can regulate receptor signaling, impacting receptor turnover and trafficking. Core fucosyl...

Full description

Saved in:
Bibliographic Details
Main Authors: Harrison Sudholz, Xiangpeng Meng, Hae-Young Park, Zihan Shen, Iva Nikolic, Joseph Cursons, Ethan D. Goddard-Borger, Iona S. Schuster, Christopher E. Andoniou, Mariapia A. Degli-Esposti, Nichollas E. Scott, Michael Chopin, Jai Rautela, Sebastian Scheer, Nicholas D. Huntington
Format: Article
Language:English
Published: Elsevier 2025-08-01
Series:Cell Reports
Subjects:
Online Access:http://www.sciencedirect.com/science/article/pii/S2211124725008721
Tags: Add Tag
No Tags, Be the first to tag this record!
_version_ 1849248174514896896
author Harrison Sudholz
Xiangpeng Meng
Hae-Young Park
Zihan Shen
Iva Nikolic
Joseph Cursons
Ethan D. Goddard-Borger
Iona S. Schuster
Christopher E. Andoniou
Mariapia A. Degli-Esposti
Nichollas E. Scott
Michael Chopin
Jai Rautela
Sebastian Scheer
Nicholas D. Huntington
author_facet Harrison Sudholz
Xiangpeng Meng
Hae-Young Park
Zihan Shen
Iva Nikolic
Joseph Cursons
Ethan D. Goddard-Borger
Iona S. Schuster
Christopher E. Andoniou
Mariapia A. Degli-Esposti
Nichollas E. Scott
Michael Chopin
Jai Rautela
Sebastian Scheer
Nicholas D. Huntington
author_sort Harrison Sudholz
collection DOAJ
description Summary: Natural killer (NK) cell homeostasis and effector functions require context-dependent signaling via numerous receptors, including the interleukin-15 receptor (IL-15R). Post-translational modifications can regulate receptor signaling, impacting receptor turnover and trafficking. Core fucosylation is one such modification known to impact receptor expression and is uniquely mediated by fucosyltransferase 8 (FUT8). We identified FUT8 as an essential gene required for IL-15R responsiveness in a human NK cell genome-wide CRISPR screen. To further validate core fucosylation in IL-15R signaling and NK cell biology, mice lacking Fut8 in NK cells (Fut8fl/flNcr1cre/+) were generated. The loss of core fucose in murine NK cells resulted in severe NK cell lymphopenia, with a reduction in IL-15Rβ (IL-2RB/CD122) expression, impairing in vivo homeostatic proliferation. The loss of FUT8 also decreased NK cell cytotoxicity, tumor immunity, and early viral immunity. Taking these results together, we have identified FUT8 as a key modulator of NK cell biology by regulating their development, IL-15R expression, and signaling.
format Article
id doaj-art-82653823149b43f1a04e8b92d865f5c4
institution Kabale University
issn 2211-1247
language English
publishDate 2025-08-01
publisher Elsevier
record_format Article
series Cell Reports
spelling doaj-art-82653823149b43f1a04e8b92d865f5c42025-08-20T03:58:00ZengElsevierCell Reports2211-12472025-08-0144811610110.1016/j.celrep.2025.116101Core fucosylation of IL-2RB is required for natural killer cell homeostasisHarrison Sudholz0Xiangpeng Meng1Hae-Young Park2Zihan Shen3Iva Nikolic4Joseph Cursons5Ethan D. Goddard-Borger6Iona S. Schuster7Christopher E. Andoniou8Mariapia A. Degli-Esposti9Nichollas E. Scott10Michael Chopin11Jai Rautela12Sebastian Scheer13Nicholas D. Huntington14Department of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; Division of Immunology and Molecular Medicine, Department of Molecular and Cell Biology, University of California, Berkeley, Berkeley, CA 94720, USADepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, AustraliaDepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, AustraliaDepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, AustraliaoNKo-Innate Pty., Ltd., 27 Norwood Cres, Moonee Ponds, VIC 3039, AustraliaoNKo-Innate Pty., Ltd., 27 Norwood Cres, Moonee Ponds, VIC 3039, AustraliaACRF, Chemical Biology Division, The Walter and Eliza Hall Institute of Medical Research, Parkville, VIC 3052, Australia; Department of Medical Biology, University of Melbourne, Parkville, VIC 3010, AustraliaInfection and Immunity Program and Department of Microbiology Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; Centre for Experimental Immunology, Lions Eye Institute, Nedlands, WA 6009, AustraliaInfection and Immunity Program and Department of Microbiology Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; Centre for Experimental Immunology, Lions Eye Institute, Nedlands, WA 6009, AustraliaInfection and Immunity Program and Department of Microbiology Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; Centre for Experimental Immunology, Lions Eye Institute, Nedlands, WA 6009, AustraliaDepartment of Microbiology and Immunology, The Peter Doherty Institute for Infection and Immunity, University of Melbourne, Parkville, VIC 3010, AustraliaDepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, AustraliaoNKo-Innate Pty., Ltd., 27 Norwood Cres, Moonee Ponds, VIC 3039, AustraliaDepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; Department of Infection and Immunity, Luxembourg Institute of Health, 4354 Esch-sur-Alzette, LuxembourgDepartment of Biochemistry and Molecular Biology, Biomedicine Discovery Institute, Monash University, Clayton, VIC 3800, Australia; oNKo-Innate Pty., Ltd., 27 Norwood Cres, Moonee Ponds, VIC 3039, Australia; Corresponding authorSummary: Natural killer (NK) cell homeostasis and effector functions require context-dependent signaling via numerous receptors, including the interleukin-15 receptor (IL-15R). Post-translational modifications can regulate receptor signaling, impacting receptor turnover and trafficking. Core fucosylation is one such modification known to impact receptor expression and is uniquely mediated by fucosyltransferase 8 (FUT8). We identified FUT8 as an essential gene required for IL-15R responsiveness in a human NK cell genome-wide CRISPR screen. To further validate core fucosylation in IL-15R signaling and NK cell biology, mice lacking Fut8 in NK cells (Fut8fl/flNcr1cre/+) were generated. The loss of core fucose in murine NK cells resulted in severe NK cell lymphopenia, with a reduction in IL-15Rβ (IL-2RB/CD122) expression, impairing in vivo homeostatic proliferation. The loss of FUT8 also decreased NK cell cytotoxicity, tumor immunity, and early viral immunity. Taking these results together, we have identified FUT8 as a key modulator of NK cell biology by regulating their development, IL-15R expression, and signaling.http://www.sciencedirect.com/science/article/pii/S2211124725008721CP: Immunology
spellingShingle Harrison Sudholz
Xiangpeng Meng
Hae-Young Park
Zihan Shen
Iva Nikolic
Joseph Cursons
Ethan D. Goddard-Borger
Iona S. Schuster
Christopher E. Andoniou
Mariapia A. Degli-Esposti
Nichollas E. Scott
Michael Chopin
Jai Rautela
Sebastian Scheer
Nicholas D. Huntington
Core fucosylation of IL-2RB is required for natural killer cell homeostasis
Cell Reports
CP: Immunology
title Core fucosylation of IL-2RB is required for natural killer cell homeostasis
title_full Core fucosylation of IL-2RB is required for natural killer cell homeostasis
title_fullStr Core fucosylation of IL-2RB is required for natural killer cell homeostasis
title_full_unstemmed Core fucosylation of IL-2RB is required for natural killer cell homeostasis
title_short Core fucosylation of IL-2RB is required for natural killer cell homeostasis
title_sort core fucosylation of il 2rb is required for natural killer cell homeostasis
topic CP: Immunology
url http://www.sciencedirect.com/science/article/pii/S2211124725008721
work_keys_str_mv AT harrisonsudholz corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT xiangpengmeng corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT haeyoungpark corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT zihanshen corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT ivanikolic corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT josephcursons corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT ethandgoddardborger corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT ionasschuster corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT christophereandoniou corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT mariapiaadegliesposti corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT nichollasescott corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT michaelchopin corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT jairautela corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT sebastianscheer corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis
AT nicholasdhuntington corefucosylationofil2rbisrequiredfornaturalkillercellhomeostasis