Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.

<h4>Background</h4>Despite a historical association with poor tolerability, a comprehensive review on safety of antileishmanial chemotherapies is lacking. We carried out an update of a previous systematic review of all published clinical trials in visceral leishmaniasis (VL) from 1980 to...

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Main Authors: Sauman Singh-Phulgenda, Prabin Dahal, Roland Ngu, Brittany J Maguire, Alice Hawryszkiewycz, Sumayyah Rashan, Matthew Brack, Christine M Halleux, Fabiana Alves, Kasia Stepniewska, Piero L Olliaro, Philippe J Guerin
Format: Article
Language:English
Published: Public Library of Science (PLoS) 2021-03-01
Series:PLoS Neglected Tropical Diseases
Online Access:https://journals.plos.org/plosntds/article/file?id=10.1371/journal.pntd.0009302&type=printable
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author Sauman Singh-Phulgenda
Prabin Dahal
Roland Ngu
Brittany J Maguire
Alice Hawryszkiewycz
Sumayyah Rashan
Matthew Brack
Christine M Halleux
Fabiana Alves
Kasia Stepniewska
Piero L Olliaro
Philippe J Guerin
author_facet Sauman Singh-Phulgenda
Prabin Dahal
Roland Ngu
Brittany J Maguire
Alice Hawryszkiewycz
Sumayyah Rashan
Matthew Brack
Christine M Halleux
Fabiana Alves
Kasia Stepniewska
Piero L Olliaro
Philippe J Guerin
author_sort Sauman Singh-Phulgenda
collection DOAJ
description <h4>Background</h4>Despite a historical association with poor tolerability, a comprehensive review on safety of antileishmanial chemotherapies is lacking. We carried out an update of a previous systematic review of all published clinical trials in visceral leishmaniasis (VL) from 1980 to 2019 to document any reported serious adverse events (SAEs).<h4>Methods</h4>For this updated systematic review, we searched the following databases from 1st Jan 2016 through 2nd of May 2019: PUBMED, Embase, Scopus, Web of Science, Cochrane, clinicaltrials.gov, WHO ICTRP, and the Global Index Medicus. We included randomised and non-randomised interventional studies aimed at assessing therapeutic efficacy and extracted the number of SAEs reported within the first 30 days of treatment initiation. The incidence rate of death (IRD) from individual treatment arms were combined in a meta-analysis using random effects Poisson regression.<h4>Results</h4>We identified 157 published studies enrolling 35,376 patients in 347 treatment arms. Pentavalent antimony was administered in 74 (21.3%), multiple-dose liposomal amphotericin B (L-AmB) in 52 (15.0%), amphotericin b deoxycholate in 51 (14.7%), miltefosine in 33 (9.5%), amphotericin b fat/lipid/colloid/cholesterol in 31 (8.9%), and single-dose L-AmB in 17 (4.9%) arms. There was a total of 804 SAEs reported of which 793 (including 428 deaths) were extracted at study arm level (11 SAEs were reported at study level only). During the first 30 days, there were 285 (66.6%) deaths with the overall IRD estimated at 0.068 [95% confidence interval (CI): 0.041-0.114; I2 = 81.4%; 95% prediction interval (PI): 0.001-2.779] per 1,000 person-days at risk; the rate was 0.628 [95% CI: 0.368-1.021; I2 = 82.5%] in Eastern Africa, and 0.041 [95% CI: 0.021-0.081; I2 = 68.1%] in the Indian Subcontinent. In 21 study arms which clearly indicated allowing the inclusion of patients with HIV co-infections the IRD was 0.575 [95% CI: 0.244-1.355; I2 = 91.9%] compared to 0.043 [95% CI: 0.020-0.090; I2 = 62.5%] in 160 arms which excluded HIV co-infections.<h4>Conclusion</h4>Mortality within the first 30 days of VL treatment initiation was a rarely reported event in clinical trials with an overall estimated rate of 0.068 deaths per 1,000 person-days at risk, though it varied across regions and patient populations. These estimates may serve as a benchmark for future trials against which mortality data from prospective and pharmacovigilance studies can be compared. The methodological limitations exposed by our review support the need to assemble individual patient data (IPD) to conduct robust IPD meta-analyses and generate stronger evidence from existing trials to support treatment guidelines and guide future research.
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1935-2735
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spelling doaj-art-4a2c34e3f3f84a47ac1b2a35a2b3e6a72025-08-20T03:47:07ZengPublic Library of Science (PLoS)PLoS Neglected Tropical Diseases1935-27271935-27352021-03-01153e000930210.1371/journal.pntd.0009302Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.Sauman Singh-PhulgendaPrabin DahalRoland NguBrittany J MaguireAlice HawryszkiewyczSumayyah RashanMatthew BrackChristine M HalleuxFabiana AlvesKasia StepniewskaPiero L OlliaroPhilippe J Guerin<h4>Background</h4>Despite a historical association with poor tolerability, a comprehensive review on safety of antileishmanial chemotherapies is lacking. We carried out an update of a previous systematic review of all published clinical trials in visceral leishmaniasis (VL) from 1980 to 2019 to document any reported serious adverse events (SAEs).<h4>Methods</h4>For this updated systematic review, we searched the following databases from 1st Jan 2016 through 2nd of May 2019: PUBMED, Embase, Scopus, Web of Science, Cochrane, clinicaltrials.gov, WHO ICTRP, and the Global Index Medicus. We included randomised and non-randomised interventional studies aimed at assessing therapeutic efficacy and extracted the number of SAEs reported within the first 30 days of treatment initiation. The incidence rate of death (IRD) from individual treatment arms were combined in a meta-analysis using random effects Poisson regression.<h4>Results</h4>We identified 157 published studies enrolling 35,376 patients in 347 treatment arms. Pentavalent antimony was administered in 74 (21.3%), multiple-dose liposomal amphotericin B (L-AmB) in 52 (15.0%), amphotericin b deoxycholate in 51 (14.7%), miltefosine in 33 (9.5%), amphotericin b fat/lipid/colloid/cholesterol in 31 (8.9%), and single-dose L-AmB in 17 (4.9%) arms. There was a total of 804 SAEs reported of which 793 (including 428 deaths) were extracted at study arm level (11 SAEs were reported at study level only). During the first 30 days, there were 285 (66.6%) deaths with the overall IRD estimated at 0.068 [95% confidence interval (CI): 0.041-0.114; I2 = 81.4%; 95% prediction interval (PI): 0.001-2.779] per 1,000 person-days at risk; the rate was 0.628 [95% CI: 0.368-1.021; I2 = 82.5%] in Eastern Africa, and 0.041 [95% CI: 0.021-0.081; I2 = 68.1%] in the Indian Subcontinent. In 21 study arms which clearly indicated allowing the inclusion of patients with HIV co-infections the IRD was 0.575 [95% CI: 0.244-1.355; I2 = 91.9%] compared to 0.043 [95% CI: 0.020-0.090; I2 = 62.5%] in 160 arms which excluded HIV co-infections.<h4>Conclusion</h4>Mortality within the first 30 days of VL treatment initiation was a rarely reported event in clinical trials with an overall estimated rate of 0.068 deaths per 1,000 person-days at risk, though it varied across regions and patient populations. These estimates may serve as a benchmark for future trials against which mortality data from prospective and pharmacovigilance studies can be compared. The methodological limitations exposed by our review support the need to assemble individual patient data (IPD) to conduct robust IPD meta-analyses and generate stronger evidence from existing trials to support treatment guidelines and guide future research.https://journals.plos.org/plosntds/article/file?id=10.1371/journal.pntd.0009302&type=printable
spellingShingle Sauman Singh-Phulgenda
Prabin Dahal
Roland Ngu
Brittany J Maguire
Alice Hawryszkiewycz
Sumayyah Rashan
Matthew Brack
Christine M Halleux
Fabiana Alves
Kasia Stepniewska
Piero L Olliaro
Philippe J Guerin
Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
PLoS Neglected Tropical Diseases
title Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
title_full Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
title_fullStr Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
title_full_unstemmed Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
title_short Serious adverse events following treatment of visceral leishmaniasis: A systematic review and meta-analysis.
title_sort serious adverse events following treatment of visceral leishmaniasis a systematic review and meta analysis
url https://journals.plos.org/plosntds/article/file?id=10.1371/journal.pntd.0009302&type=printable
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