A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine

Introduction Alice in Wonderland Syndrome (AIWS) is an uncommon condition manifesting visual and somatosensory disturbances in which patients may perceive objects, including their own bodies, as larger or smaller than they are. In adults, AIWS typically is associated with migraine and epilepsy but h...

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Main Authors: Wen X. Jiang, Jonathan G. Leung, PharmD, Danielle N. Carlson, APRN, CNS-BC, Jeffrey P. Staab, MD, MS
Format: Article
Language:English
Published: American Association of Psychiatric Pharmacists 2025-08-01
Series:Mental Health Clinician
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Online Access:https://theijpt.org/doi/pdf/10.9740/mhc.2025.08.208
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author Wen X. Jiang
Jonathan G. Leung, PharmD
Danielle N. Carlson, APRN, CNS-BC
Jeffrey P. Staab, MD, MS
author_facet Wen X. Jiang
Jonathan G. Leung, PharmD
Danielle N. Carlson, APRN, CNS-BC
Jeffrey P. Staab, MD, MS
author_sort Wen X. Jiang
collection DOAJ
description Introduction Alice in Wonderland Syndrome (AIWS) is an uncommon condition manifesting visual and somatosensory disturbances in which patients may perceive objects, including their own bodies, as larger or smaller than they are. In adults, AIWS typically is associated with migraine and epilepsy but has been reported as an adverse effect of topiramate, which is used to treat both illnesses, making it difficult to ascertain whether illness or medication causes altered perceptions. Reported is a case of topiramate-associated AIWS, which adds to the limited reports published on this unique phenomenon. Case Report A 40-year-old woman admitted to a 3-week pain rehabilitation program to treat chronic migraine reported macrosomatognosia that she retrospectively recalled beginning during titration of topiramate. The symptoms of AIWS resolved after the topiramate was discontinued. An assessment with the Naranjo ADR Probability Scale indicated a possible association between topiramate and macrosomatognosia. Discussion In this patient with migraine, the onset of AIWS coincided with titration of topiramate, providing a clue that its emergence may have been an adverse drug reaction rather than the underlying illness. Consistent with previous reports, AIWS resolved shortly after topiramate was discontinued, lending credence to this conclusion. However, the mechanism of AIWS is unknown and may be multifactorial, leaving the possibility that migraine predisposed the patient to develop AIWS from topiramate. Conclusion The long association of AIWS with migraine and epilepsy makes it possible that cases caused by medications used to treat these illnesses, like topiramate, are underreported. Awareness of the temporal relationships between the course of illness and the timing of drug therapy can help guide the recognition of AIWS as a potential adverse event.
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spelling doaj-art-3115b24fa23749b98ab01b3bda8055a92025-08-23T16:55:39ZengAmerican Association of Psychiatric PharmacistsMental Health Clinician2168-97092025-08-0115420821310.9740/mhc.2025.08.208i2168-9709-15-4-208A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraineWen X. Jiang0https://orcid.org/0009-0009-6994-5612Jonathan G. Leung, PharmD1https://orcid.org/0000-0003-3836-9375Danielle N. Carlson, APRN, CNS-BC2https://orcid.org/0009-0009-9724-9534Jeffrey P. Staab, MD, MS3https://orcid.org/0000-0002-1516-31311 PharmD Candidate, University of Florida, Gainesville, Florida2 (Corresponding author) Pharmacist, Mayo Clinic, Rochester, Minnesota3 Advanced Practice CNS Provider, Mayo Clinic, Rochester, Minnesota4 Professor and Chair, Mayo Clinic, Rochester, MinnesotaIntroduction Alice in Wonderland Syndrome (AIWS) is an uncommon condition manifesting visual and somatosensory disturbances in which patients may perceive objects, including their own bodies, as larger or smaller than they are. In adults, AIWS typically is associated with migraine and epilepsy but has been reported as an adverse effect of topiramate, which is used to treat both illnesses, making it difficult to ascertain whether illness or medication causes altered perceptions. Reported is a case of topiramate-associated AIWS, which adds to the limited reports published on this unique phenomenon. Case Report A 40-year-old woman admitted to a 3-week pain rehabilitation program to treat chronic migraine reported macrosomatognosia that she retrospectively recalled beginning during titration of topiramate. The symptoms of AIWS resolved after the topiramate was discontinued. An assessment with the Naranjo ADR Probability Scale indicated a possible association between topiramate and macrosomatognosia. Discussion In this patient with migraine, the onset of AIWS coincided with titration of topiramate, providing a clue that its emergence may have been an adverse drug reaction rather than the underlying illness. Consistent with previous reports, AIWS resolved shortly after topiramate was discontinued, lending credence to this conclusion. However, the mechanism of AIWS is unknown and may be multifactorial, leaving the possibility that migraine predisposed the patient to develop AIWS from topiramate. Conclusion The long association of AIWS with migraine and epilepsy makes it possible that cases caused by medications used to treat these illnesses, like topiramate, are underreported. Awareness of the temporal relationships between the course of illness and the timing of drug therapy can help guide the recognition of AIWS as a potential adverse event.https://theijpt.org/doi/pdf/10.9740/mhc.2025.08.208topiramateadverse drug reactionmigraine headachealice in wonderland syndromemacrosomatognosia
spellingShingle Wen X. Jiang
Jonathan G. Leung, PharmD
Danielle N. Carlson, APRN, CNS-BC
Jeffrey P. Staab, MD, MS
A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
Mental Health Clinician
topiramate
adverse drug reaction
migraine headache
alice in wonderland syndrome
macrosomatognosia
title A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
title_full A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
title_fullStr A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
title_full_unstemmed A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
title_short A case of Alice in Wonderland Syndrome associated with topiramate in a patient with vestibular migraine
title_sort case of alice in wonderland syndrome associated with topiramate in a patient with vestibular migraine
topic topiramate
adverse drug reaction
migraine headache
alice in wonderland syndrome
macrosomatognosia
url https://theijpt.org/doi/pdf/10.9740/mhc.2025.08.208
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