JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain

Abstract Midbrain dopamine (mDA) neurons participate in a wide range of brain functions through an intricate regulation of DA biosynthesis. The epigenetic factors and mechanisms in this process are not well understood. Here we report that histone demethylase JMJD3 is a critical regulator for DA bios...

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Main Authors: Xi-Biao He, Fang Guo, Wei Zhang, Jiacheng Fan, Weidong Le, Qi Chen, Yongjun Ma, Yong Zheng, Sang-Hun Lee, Hui-Jing Wang, Yi Wu, Qinming Zhou, Rui Yang
Format: Article
Language:English
Published: BMC 2024-12-01
Series:Acta Neuropathologica Communications
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Online Access:https://doi.org/10.1186/s40478-024-01912-x
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author Xi-Biao He
Fang Guo
Wei Zhang
Jiacheng Fan
Weidong Le
Qi Chen
Yongjun Ma
Yong Zheng
Sang-Hun Lee
Hui-Jing Wang
Yi Wu
Qinming Zhou
Rui Yang
author_facet Xi-Biao He
Fang Guo
Wei Zhang
Jiacheng Fan
Weidong Le
Qi Chen
Yongjun Ma
Yong Zheng
Sang-Hun Lee
Hui-Jing Wang
Yi Wu
Qinming Zhou
Rui Yang
author_sort Xi-Biao He
collection DOAJ
description Abstract Midbrain dopamine (mDA) neurons participate in a wide range of brain functions through an intricate regulation of DA biosynthesis. The epigenetic factors and mechanisms in this process are not well understood. Here we report that histone demethylase JMJD3 is a critical regulator for DA biosynthesis in adult mouse mDA neurons. Mice carrying Jmjd3 conditional knockout or undergoing pharmaceutical inhibition of JMJD3 showed consistent reduction of DA content in midbrain and striatum. Histological examination of both mice confirmed that TH and NURR1, two key molecules in DA biosynthesis pathway, were decreased in mDA neurons. Mechanistic experiments in vivo and in vitro further demonstrated that the transcriptions of Th and Nurr1 in mDA neurons were suppressed by JMJD3 deficiency, because of increased repressive H3K27me3 and attenuated bindings of JMJD3 and NURR1 on the promoters of both genes. On behavioral level, a significant prolonged inflammation-induced mechanical hyperalgesia was found in conditional knockout mice regardless of sex and age, whereas motor function appeared to be intact. Our findings establish a novel link between DA level in mDA neurons with intrinsic JMJD3 activity, and suggest prolonged chronic inflammatory pain as a major loss-of-function consequence.
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institution Kabale University
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publishDate 2024-12-01
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series Acta Neuropathologica Communications
spelling doaj-art-1a4be39c57f54c89a10a613e3e646a442024-12-29T12:51:50ZengBMCActa Neuropathologica Communications2051-59602024-12-0112111510.1186/s40478-024-01912-xJMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory painXi-Biao He0Fang Guo1Wei Zhang2Jiacheng Fan3Weidong Le4Qi Chen5Yongjun Ma6Yong Zheng7Sang-Hun Lee8Hui-Jing Wang9Yi Wu10Qinming Zhou11Rui Yang12Laboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesState Key Laboratory of Microbial Metabolism, School of Life Science and Biotechnology, Shanghai Jiao Tong UniversityLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesCenter for Translational Medicine, Shanghai University of Medicine & Health SciencesLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesDepartment of Biochemistry and Molecular Biology, College of Medicine, Hanyang UniversityLaboratory of Neuropsychopharmacology, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesDepartment of Neurology, Ruijin Hospital, Shanghai Jiao Tong University School of MedicineLaboratory of Stem Cell Biology and Epigenetics, School of Basic Medical Sciences, Shanghai University of Medicine & Health SciencesAbstract Midbrain dopamine (mDA) neurons participate in a wide range of brain functions through an intricate regulation of DA biosynthesis. The epigenetic factors and mechanisms in this process are not well understood. Here we report that histone demethylase JMJD3 is a critical regulator for DA biosynthesis in adult mouse mDA neurons. Mice carrying Jmjd3 conditional knockout or undergoing pharmaceutical inhibition of JMJD3 showed consistent reduction of DA content in midbrain and striatum. Histological examination of both mice confirmed that TH and NURR1, two key molecules in DA biosynthesis pathway, were decreased in mDA neurons. Mechanistic experiments in vivo and in vitro further demonstrated that the transcriptions of Th and Nurr1 in mDA neurons were suppressed by JMJD3 deficiency, because of increased repressive H3K27me3 and attenuated bindings of JMJD3 and NURR1 on the promoters of both genes. On behavioral level, a significant prolonged inflammation-induced mechanical hyperalgesia was found in conditional knockout mice regardless of sex and age, whereas motor function appeared to be intact. Our findings establish a novel link between DA level in mDA neurons with intrinsic JMJD3 activity, and suggest prolonged chronic inflammatory pain as a major loss-of-function consequence.https://doi.org/10.1186/s40478-024-01912-xDopamine biosynthesisMidbrain dopamine neuronTranscriptional regulationChronic inflammatory painEpigenetic control
spellingShingle Xi-Biao He
Fang Guo
Wei Zhang
Jiacheng Fan
Weidong Le
Qi Chen
Yongjun Ma
Yong Zheng
Sang-Hun Lee
Hui-Jing Wang
Yi Wu
Qinming Zhou
Rui Yang
JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
Acta Neuropathologica Communications
Dopamine biosynthesis
Midbrain dopamine neuron
Transcriptional regulation
Chronic inflammatory pain
Epigenetic control
title JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
title_full JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
title_fullStr JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
title_full_unstemmed JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
title_short JMJD3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
title_sort jmjd3 deficiency disturbs dopamine biosynthesis in midbrain and aggravates chronic inflammatory pain
topic Dopamine biosynthesis
Midbrain dopamine neuron
Transcriptional regulation
Chronic inflammatory pain
Epigenetic control
url https://doi.org/10.1186/s40478-024-01912-x
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